A male camel, aged 11 years, had a solid and mobile mass on the left side of the upper jaw. X-ray imaging showed a distinct, radiopaque and oval-shaped mass at the level of the parotid duct. The condition was diagnosed as left parotid duct sialolithiasis. The sialolith was surgically removed through a transcutaneous approach. The male camel had uneventful recovery without complications. This paper reported a rare case of sialolithiasis in dromedary camel and described its clinical presentation, diagnostic findings, and surgical treatment.